Publication: Abnormal layering of muscularis propria as a cause of chronic intestinal pseudo-obstruction: A case report and literature review
Issued Date
2015-06-14
Resource Type
ISSN
22192840
10079327
10079327
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2-s2.0-84930835461
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Mahidol University
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SCOPUS
Bibliographic Citation
World Journal of Gastroenterology. Vol.21, No.22 (2015), 7059-7064
Suggested Citation
Napat Angkathunyakul, Suporn Treepongkaruna, Sani Molagool, Nichanan Ruangwattanapaisarn Abnormal layering of muscularis propria as a cause of chronic intestinal pseudo-obstruction: A case report and literature review. World Journal of Gastroenterology. Vol.21, No.22 (2015), 7059-7064. doi:10.3748/wjg.v21.i22.7059 Retrieved from: https://repository.li.mahidol.ac.th/handle/20.500.14594/36404
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Title
Abnormal layering of muscularis propria as a cause of chronic intestinal pseudo-obstruction: A case report and literature review
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Abstract
© 2015 Baishideng Publishing Group Inc. All rights reserved. Visceral myopathy is one of the causes of chronic intestinal pseudo-obstruction. Most cases pathologically reveal degenerative changes of myocytes or muscularis propia atrophy and fibrosis. Abnormal layering of muscularis propria is extremely rare. We report a case of a 9-mo-old Thai male baby who presented with chronic intestinal pseudo-obstruction. Histologic findings showed abnormal layering of small intestinal muscularis propria with an additional oblique layer and aberrant muscularization in serosa. The patient also had a short small bowel without malrotation, brachydactyly, and absence of the 2nd to 4th middle phalanges of both hands. The patient was treated with cisapride and combined parenteral and enteral nutritional support. He had gradual clinical improvement and gained body weight. Subsequently, the parenteral nutrition was discontinued. The previously reported cases are reviewed and discussed.